Poster Presentation 43rd Lorne Genome Conference 2022

Y chromosome condensation by a novel PML-nuclear body (#161)

Nayla Leon Carlos 1 , Stefan Bagheri-Fam 1 , Sophia Astbury 1 , Emily Frost 1 , Lee Wong 2 , Vincent Harley 1
  1. Hudson Institute of Medical Research, Melbourne, VIC, Australia
  2. Department of Biochemistry and Molecular Biology, Monash University, Clayton, VIC, Australia

For autosomes, major satellite DNA forms chromocenters at pericentromeric heterochromatin where Histone 3 is phosphorylated (PH3) and chromosome condensation is initiated. However, the mouse Y chromosome lacks major satellite DNA, so how the mouse Y initiates chromosome condensation is not known.

 

Immuno-FISH showed the Sertoli cell nucleus of fetal mouse testes contains a single PML nuclear body enriched for GATA4 (GATA4-PML-NB). Also in the GATA4-PML-NB is Y chromosome region comprising GATA4 DNA binding motifs, and heterochromatin protein 1 alpha (HP1a), PH3 and ATRX chromatin remodeller.

 

ATR-X syndrome is a condition that affects boys characterised by intellectual disability, alpha thalassemia, and XY male-to-female sex reversal1. We generated mice with Atrx inactivated in Sertoli cells (Atrx KO) to mimic the gonadal phenotype of ATR-X syndrome. These mice show testicular dysgenesis due to cell cycle arrest at G2 and apoptosis of fetal Sertoli cells2.

 

In Atrx KO testes, the GATA4-PML-NBs are up to 3-fold larger (~3mm), lack HP1a and PH3 expression, and show double-strand DNA breaks (gH2AX), indicative of a failure in chromosome condensation.

 

In summary Y chromosome condensation in mouse Sertoli cells requires ATRX at a single unique PML-NB, rich in GATA4. The GATA4-PML-NB marks a chromatin region on the mouse Y chromosome that might function as a chromocenter. Analogous to major satellite DNA on autosome where chromosome condensation initiates, GATA-rich sequences on Y chromosome might the nucleate Y chromosome condensation.

  1. Leon, N. and Harley V. Human Genetics (2021-in press) https://doi.org/10.1007/s00439-021-02361-5
  2. Bagheri-Fam S, Argentaro A, et al. 2011. HumMolGenet 20:2213-24.